METAP1mutation is a novel candidate for autosomal recessive intellectual disability


ÇAĞLAYAN A. O., Aktar F., Bilguvar K., Baranoski J. F., Akgumus G. T., Harmanci A. S., ...More

JOURNAL OF HUMAN GENETICS, vol.66, no.2, pp.215-218, 2021 (SCI-Expanded, Scopus)

  • Publication Type: Article / Article
  • Volume: 66 Issue: 2
  • Publication Date: 2021
  • Doi Number: 10.1038/s10038-020-0820-0
  • Journal Name: JOURNAL OF HUMAN GENETICS
  • Journal Indexes: Science Citation Index Expanded (SCI-EXPANDED), Scopus, Academic Search Premier, BIOSIS, CAB Abstracts, EMBASE, MEDLINE
  • Page Numbers: pp.215-218
  • Dokuz Eylül University Affiliated: Yes

Abstract

Intellectual disability (ID) is a genetic and clinically heterogeneous common disease and underlying molecular pathogenesis can frequently not be identified by whole-exome/genome testing. Here, we report four siblings born to a consanguineous union who presented with intellectual disability and discuss theMETAP1pathway as a novel etiology of ID. Genomic analyses demonstrated that patients harbor a novel homozygous nonsense mutation in the geneMETAP1.METAP1codes for methionine aminopeptidase 1 (MetAP1) which oversees the co-translational excision of the first methionine remnants in eukaryotes. The loss-of-function mutations to this gene may result in a defect in the translation of many essential proteins within a cell. Improper neuronal function resulting from this loss of essential proteins could lead to neurologic impairment and ID.